Prosthetic dental management of a patient with anhidrotic ectodermal dysplasia. A Case Report.

Abstract

Introduction: Ectodermal dysplasia (ED) comprises a broad group of genetic disorders characterized by alterations of the structures derived from the ectoderm, including those of the stomatognathic system. Case Report: The present article aims to report the prosthetic management of a patient with anhidrotic ectodermal dysplasia. A male patient diagnosed with ED who attended the dental consultation displaying oligodontia; underdeveloped alveolar ridges were observed. Results: The established treatment consisted of the adaptation of implant-supported fixed full-arch prosthesis designed through CAD-CAM technology for the lower jaw and of a removable partial prosthesis with muco-dental support for the upper jaw. The dental approach of patients with ED is based on a correct analysis of the facial characteristics and stomatological conditions of each subject. Conclusion: A multidisciplinary approach is mandatory due to the biological and functional complexity in biomechanical terms of these individuals.

References

1. Reyes-Reali J, Mendoza-Ramos MI, Garrido-Guerrero E, Méndez-Catalá CF, Méndez-Cruz AR, Pozo-Molina G. Hypohidrotic ectodermal dysplasia: clinical and molecular review. Int J Dermatol [Internet]. 2018;57(8):965–72.
2. Gurcan AT, Seymen F, Yardimci S. Case series of ectodermal dysplasia and evaluation of oral findings: A literature review. Ann Med Res. 2020;27(1):420–5.
3. Bhakta P, Barthunia B, Nigam H, Pawar P. Ectodermal dysplasia - A rare case report. J Fam Med Prim Care [Internet]. 2019;8(9):3054–6.
4. Ghoveizi R, Siadat H, Nikzad S, Ommati Shabestari G, Soleimani Shayesteh Y. Full mouth rehabilitation of an ectodermal dysplasia patient with implant-supported prostheses: a clinical report. J Dent. 2013;10(3):283–8.
5. Schnabl D, Grunert I, Schmuth M, Kapferer-Seebacher I. Prosthetic rehabilitation of patients with hypohidrotic ectodermal dysplasia: A systematic review. J Oral Rehab. 2018;45(7):555–70.
6. Kassar WM. Dental Rehabilitation of a Child with Ectodermal Dysplasia: A Case Report. Int J Clin Pediatr Dent. 2019;12(4):362–5.
7. Alnuaimi R, Mansoor M. Prosthetic rehabilitation with fixed prosthesis of a 5-year-old child with Hypohidrotic Ectodermal Dysplasia and Oligodontia: A case report. J Med Case Rep. 2019;13(1):1–6.
8. Mello BZF, Silva TC, Rios D, Machado MAAM, Valarelli FP, Oliveira TM. Mini-implants: Alternative for oral rehabilitation of a child with ectodermal dysplasia. Braz Dent J [Internet]. 2015;26(1):75–8.
9. Bhargava A, Sharma A, Popli S, Bhargava R. Prosthodontic management of a child with ectodermal dysplasia: A case report. J Indian Prosthodont Soc. 2010;10(2):137–40.
10. Mokhtari S, Mokhtari S, Lotfi A. Christ-Siemens-Touraine Syndrome: A Case Report and Review of the Literature. Case Rep Dent. 2012;2012:1–3.
11. Hekmatfar S, Jafari K, Meshki R, Badakhsh S. Dental management of ectodermal dysplasia: two clinical case reports. J Dent Res Dent Clin Dent. 2012;6(3):108–12.
12. Bagegni A, Abou-Ayash S, Rücker G, Algarny A, Att W. The influence of prosthetic material on implant and prosthetic survival of implant-supported fixed complete dentures: a systematic review and meta-analysis. J Prosthod Res. 2019;63(3):251–65.
13. Zaparolli D, Peixoto RF, Pupim D, Macedo AP, Toniollo MB, Mattos M da GC de. Photoelastic analysis of mandibular full-arch implant-supported fixed dentures made with different bar materials and manufacturing techniques. Mater Sci Eng C. 2017;81:144–7.
14. Barootchi S, Askar H, Ravidà A, Gargallo-Albiol J, Travan S WH. Long-term Clinical Outcomes and Cost-Effectiveness of Full-Arch Implant-Supported Zirconia-Based and Metal-Acrylic Fixed Dental Prostheses: A Retrospective Analysis. Int J Oral Maxillofac Implants. 2020;35(2):395–405.
15. Cicconetti A, Passaretti A, Rastelli C, Rastelli, E, Falisi G. Innovations in oral and maxillofacial surgery: biomimetics meets physiology. J Biol Regul Homeost Agents. 2019;33(5):1609–13.
16. Sirandoni D, Leal E, Weber B, Noritomi PY, Fuentes R, Borie E. Effect of Different Framework Materials in Implant-Supported Fixed Mandibular Prostheses: A Finite Element Analysis. Int J Oral Maxillofac Implants. 2019;34(6):e107–14.
17. Van Heumen CCM, Kreulen CM, Creugers NHJ. Clinical studies of fiber-reinforced resin-bonded fixed partial dentures: A systematic review. European J Oral Scie. 2009;117(1):1-6.
Published
2021-08-31
How to Cite
HERNÁNDEZ-GONZÁLEZ, Daniel; OROZCO-PÁEZ, Jennifer. Prosthetic dental management of a patient with anhidrotic ectodermal dysplasia. A Case Report.. Journal of Oral Research, [S.l.], v. 10, n. 4, p. 1-6, aug. 2021. ISSN 0719-2460. Available at: <https://www.joralres.com/index.php/JOralRes/article/view/joralres.2021.057>. Date accessed: 14 oct. 2024. doi: https://doi.org/10.17126/joralres.2021.057.
Section
Cases